Chronic intestinal pseudo-obstruction due to lymphocytic intestinal leiomyositis: Case report and literature review

Keiichi Uchida, Kohei Otake, Mikihiro Inoue, Yuhki Koike, Kohei Matsushita, Toshimitsu Araki, Yoshiki Okita, Koji Tanaka, Katsunori Uchiad, Noriko Yodoya, Shotaro Iwamoto, Katsuhiro Arai, Masato Kusunoki

Research output: Contribution to journalArticlepeer-review

3 Citations (Scopus)

Abstract

Lymphocytic intestinal leiomyositis is a rare entity, which causes chronic intestinal pseudo-obstruction (CIPO) in children. We present the first case of a boy who had pure red cell anemia 1 year before onset. Prolonged ileus developed after gastroenteritis and the patient was diagnosed using a biopsy of the intestinal wall. Findings from the present case indicate that there are three important factors for accurate diagnosis: history of enteritis, positive serum smooth muscle antibody, and lymphocyte infiltration with muscle destruction in the muscularis propria in the intestinal wall. Earlier diagnosis and induction of immunosuppressive therapy may be essential for a better outcome.

Original languageEnglish
Pages (from-to)35-39
Number of pages5
JournalIntractable and Rare Diseases Research
Volume1
Issue number1
DOIs
Publication statusPublished - 03-2012
Externally publishedYes

All Science Journal Classification (ASJC) codes

  • Medicine(all)

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